Pediatric Gastroenterology, Hepatology & Nutrition

The Korean Society of Pediatric Gastroenterology, Hepatology and Nutrition (대한소아소화기영양학회)
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A Case of Intestinal Duplication Cyst Identified as Pathological Lead Point in a Child with Recurrent Intussusception

재발성 장중첩증 환아에서 병적 선두로 확인된 장중복 낭종 1예

  • Lee, Kun-Song (Department of Pediatrics, College of Medicine, Dankook University) ;
  • Park, Ji-Yun (Department of Pediatrics, College of Medicine, Dankook University) ;
  • Oh, Jong-Seok (Department of Pediatrics, College of Medicine, Dankook University) ;
  • Seong, In-Chang (Department of Pediatrics, College of Medicine, Dankook University) ;
  • Han, Kang-Min (Department of Pathology, College of Medicine, Dankook University) ;
  • Lee, Young-Seok (Department of Radiology, College of Medicine, Dankook University)
  • 이건송 (단국대학교 의과대학 소아과학교실) ;
  • 박지윤 (단국대학교 의과대학 소아과학교실) ;
  • 오종석 (단국대학교 의과대학 소아과학교실) ;
  • 성인창 (단국대학교 의과대학 소아과학교실) ;
  • 한강민 (단국대학교 의과대학 병리학교실) ;
  • 이영석 (단국대학교 의과대학 영상의학과교실)
  • Received : 2010.01.31
  • Accepted : 2010.03.08
  • Published : 2010.03.30
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Abstract

Intestinal duplication cysts are characterized by the attachment to some part of the gastrointestinal tract with which a blood supply is shared, and have an epithelial lining resembling some part of the alimentary tract. A 15-month-old female was admitted to our hospital with cyclic irritability, vomiting, and blood-tinged stool. The results of an ultrasound showed an ileocolic intussusception and a 1.3 cm cystic mass had double-wall sign and a Y-configuration with an adjacent ileal loop. She had a past history of two ileocolic intussusceptions. The cystic mass was considered to be a pathologic lead point, so resection and end-to-end anastomosis was performed. The gross and histologic evaluation of the specimen demonstrated a $2.4{\times}2.4$ cm cystic mass containing yellow mucoid fluid and the cyst wall was lined with intestinal and gastric mucosa and enclosed by a layer of muscle, which was shared with the adjacent ileum.

장중첩증이 재발한 15개월 여아에서 초음파 검사에서 병적 선두로 생각되는 낭성 종괴를 확인하였고 이중벽 징후와 인접한 소장 사이에 Y자 형상의 저반향 경계를 가지고 있어 중복 낭종으로 의심하였다. 이후 절제술을 시행하여 조직병리검사에서 인접한 회장과 근육층을 공유하고 낭종의 바깥쪽으로는 인접한 장 점막상피 조직과 안쪽으로는 이소성 위 점막 조직이 관찰되는 중복 낭종으로 확진되어 문헌 고찰과 함께 보고하는 바이다.

Keywords

References

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